Myocardial ultrastructure and the development of atrioventricular block in Kearns-Sayre syndrome.

نویسندگان

  • R Charles
  • S Holt
  • J M Kay
  • E J Epstein
  • J R Rees
چکیده

A right ventricular endomyocardial biopsy specimen from a 30-year-old male with chromic progressive external ophthalmoplegia, retinal pigmentation and complete atrioventricular block (Kearns-Sayre syndrome) was examined in the electron microscope. There was a proliferation of mitochondria between the myofibrils and beneath the sarcolemma. Many of the mitochondria showed morphologic abnormalities not previously described in this condition. There were associated accumulations of glycogen. A similarly affected female with left anterior hemiblock developed complete atrioventricular block at age 26 years, Despite the ultrastructural changes, clinically detectable myocardial disease is not a feature of Kearns-Sayre syndrome. However, intraventricular conduction defects show an unusually rapid progression to potentially fatal complete atrioventricular block and are an indication for prophylactic cardiac pacing.

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عنوان ژورنال:
  • Circulation

دوره 63 1  شماره 

صفحات  -

تاریخ انتشار 1981